The concomitant occurrence of tuberculosis infection within a Warthin tumor of submandibular salivary gland is extremely rare as only one case has been previously reported to best of our knowledge. Warthin tumor is an exclusive tumor of the parotid gland and involvement of submandibular gland is very rare. Tuberculous infection of the salivary gland is also very rare. We report a case of a 50 yr old male who presented with a gradually increasing swelling of left upper neck. Surgical excision was done. Histopathology revealed warthin tumor with multiple epitheloid granulomas with caseous necrosis and the patient was treated with antituberculous drugs.