Sjogren__ampersandsignlsquo;s syndrome is a slowly progressive chronic inflammatory autoimmune disease, more commonly affecting females. It is characterized by lymphocytic infiltration of exocrine glands in 40%-60% patients. It may occur alone (Primary Sjogren__ampersandsignlsquo;s) or in association with other autoimmune diseases such as Rheumatoid arthritis (RA), Scleroderma and SLE (Secondary Sjogren__ampersandsignlsquo;s). The prevalence of Primary Sjogren__ampersandsignlsquo;s syndrome (PSS) is 0.5-1% in the general population. (1, 2) Most of the PSS patients present with the signs of Keratoconjunctivitis sicca and xerostomia and in 40% of patients, extra glandular manifestations. We present a male patient aged 44 years with the manifestation of PSS, who also showed an extra glandular site involvement.